Reliability of the Charcot‐Marie‐Tooth functional outcome measure

• DOI: 10.1111/jns.12406
• Publication Date: 2020-08-10T08:35:50Z
• Authors: Paula Bray; Kayla M. D. Cornett; Timothy Estilow; Davide Pareyson; Riccardo Zuccarino; Mariola Skorupinska; Menelaos Pipis; Janet E. Sowden; Steven Scherer; Mary M. Reilly; Michael E. Shy; David N. Herrmann; Joshua Burns; Katy J. Eichinger
• Keywords: Convergent validity

The CMT-FOM is a 13-item clinical outcome assessment (COA) that measures physical ability in adults with Charcot-Marie-Tooth disease (CMT). Test-retest reliability, internal consistency and convergent validity have been established for the CMT-FOM. This current study sought to establish inter-rater reliability. Following an in-person training of six international evaluators we recruited 10 participants genetically diagnosed CMT1A, (aged 18-74 years, 6 female). Participants were evaluated using over 2 days. given at least 3 hour rest between evaluations, assessed twice each day. provision by master trainers, all 13 items exhibited excellent reliability raw scores (ICC